A multicentre Gyrate Atrophy (GACR) patient database in the UK

  • Research type

    Research Study

  • Full title

    A multicentre Gyrate Atrophy patient database in the UK

  • IRAS ID

    328438

  • Contact name

    Karolina Stepien

  • Contact email

    karolina.stepien@nca.nhs.uk

  • Sponsor organisation

    Northern Care Alliance NHS Foundation Trust

  • Duration of Study in the UK

    5 years, 11 months, 30 days

  • Research summary

    Gyrate atrophy of the choroid and retina (GACR) is a rare inborn metabolic disease. The disease is characterized by progressive deterioration of vision, which eventually leads to blindness when patients are between forty and fifty years old. However, despite the existing treatment, disease progression continues and many patients end up severely visually impaired. Little is known about the factors that play a role in GACR's prognosis. This is mainly due to a lack of research into GACR and its treatment options. Most research consists of case reports. This is also due to the very small patient population (n=25-30 in the UK) and the often late diagnosis of the clinical picture. By compiling a database of all patients in the UK who have been diagnosed with GACR, we can collect data on the clinical course of their condition, as well as genetic and biochemical parameters, in order to get an indication of the course of the clinical picture. Possibly we could correlate different gradients with mutations, treatments, or other factors that may play a role.
    In 2019, the Gyrate Atrophy Network was established in the Netherlands. It
    focuses on the advancement of research, diagnosis and treatment of this condition by close collaboration between clinicians, scientists and patient associations. Our mission is to improve the quality of care and access to multidisciplinary
    expertise for GACR patients affected by this condition. One of the objectives is the development and maintenance of a patient registry for the collection of
    historical clinical data and recruitment of patients into clinical trials. A registry for patients will allow us to delineate the medical history of dietary treated patients and answer scientific questions to develop care pathways.

  • REC name

    North West - Preston Research Ethics Committee

  • REC reference

    24/NW/0261

  • Date of REC Opinion

    20 Aug 2024

  • REC opinion

    Favourable Opinion